Spinal muscular atrophy—insights and challenges in the treatment era

E Mercuri, MC Pera, M Scoto, R Finkel… - Nature Reviews …, 2020 - nature.com
Spinal muscular atrophy (SMA) is an autosomal recessive motor neuron disease caused by
deletion or mutation of SMN1. Four subtypes exist, characterized by different clinical …

Spinal muscular atrophy: in the challenge lies a solution

B Wirth - Trends in neurosciences, 2021 - cell.com
The path from gene discovery to therapy in spinal muscular atrophy (SMA) has been a
highly challenging endeavor, but also led to one of the most successful stories in …

[HTML][HTML] Somatic Mutations in UBA1 and Severe Adult-Onset Autoinflammatory Disease

DB Beck, MA Ferrada, KA Sikora… - … England Journal of …, 2020 - Mass Medical Soc
Background Adult-onset inflammatory syndromes often manifest with overlap** clinical
features. Variants in ubiquitin-related genes, previously implicated in autoinflammatory …

Spinal muscular atrophy: from approved therapies to future therapeutic targets for personalized medicine

H Chaytow, KME Faller, YT Huang… - Cell Reports Medicine, 2021 - cell.com
Spinal muscular atrophy (SMA) is a devastating childhood motor neuron disease that, in the
most severe cases and when left untreated, leads to death within the first two years of life …

Twenty-five years of spinal muscular atrophy research: from phenotype to genotype to therapy, and what comes next

B Wirth, M Karakaya, MJ Kye… - Annual review of …, 2020 - annualreviews.org
Twenty-five years ago, the underlying genetic cause for one of the most common and
devastating inherited diseases in humans, spinal muscular atrophy (SMA), was identified …

Diverse role of survival motor neuron protein

RN Singh, MD Howell, EW Ottesen… - Biochimica et Biophysica …, 2017 - Elsevier
Abstract The multifunctional Survival Motor Neuron (SMN) protein is required for the survival
of all organisms of the animal kingdom. SMN impacts various aspects of RNA metabolism …

Emerging therapies and challenges in spinal muscular atrophy

MA Farrar, SB Park, S Vucic, KA Carey… - Annals of …, 2017 - Wiley Online Library
Spinal muscular atrophy (SMA) is a hereditary neurodegenerative disease with severity
ranging from progressive infantile paralysis and premature death (type I) to limited motor …

The role of survival motor neuron protein (SMN) in protein homeostasis

H Chaytow, YT Huang, TH Gillingwater… - Cellular and Molecular …, 2018 - Springer
Ever since loss of survival motor neuron (SMN) protein was identified as the direct cause of
the childhood inherited neurodegenerative disorder spinal muscular atrophy, significant …

Advances in therapy for spinal muscular atrophy: promises and challenges

EJN Groen, K Talbot, TH Gillingwater - Nature Reviews Neurology, 2018 - nature.com
Spinal muscular atrophy (SMA) is a devastating motor neuron disease that predominantly
affects children and represents the most common cause of hereditary infant mortality. The …

Neurocalcin delta suppression protects against spinal muscular atrophy in humans and across species by restoring impaired endocytosis

M Riessland, A Kaczmarek, S Schneider… - The American Journal of …, 2017 - cell.com
Homozygous SMN1 loss causes spinal muscular atrophy (SMA), the most common lethal
genetic childhood motor neuron disease. SMN1 encodes SMN, a ubiquitous housekee** …