Convergence and divergence of rare genetic disorders on brain phenotypes: a review

A Raznahan, H Won, DC Glahn… - JAMA psychiatry, 2022 - jamanetwork.com
Importance Rare genetic disorders modulating gene expression—as exemplified by gene
dosage disorders (GDDs)—represent a collectively common set of high-risk factors for …

[HTML][HTML] Lessons learned from neuroimaging studies of copy number variants: a systematic review

C Modenato, S Martin-Brevet, CA Moreau… - Biological …, 2021 - Elsevier
Pathogenic copy number variants (CNVs) and aneuploidies alter gene dosage and are
associated with neurodevelopmental psychiatric disorders such as autism spectrum disorder …

Rare CNVs and phenome-wide profiling highlight brain structural divergence and phenotypical convergence

J Kopal, K Kumar, K Saltoun, C Modenato… - Nature human …, 2023 - nature.com
Copy number variations (CNVs) are rare genomic deletions and duplications that can affect
brain and behaviour. Previous reports of CNV pleiotropy imply that they converge on shared …

Pervasive alterations of intra-axonal volume and network organization in young children with a 16p11. 2 deletion

AM Maillard, D Romascano, JE Villalón-Reina… - Translational …, 2024 - nature.com
Abstract Reciprocal Copy Number Variants (CNVs) at the 16p11. 2 locus confer high risk for
autism spectrum disorder (ASD) and other neurodevelopmental disorders (NDDs) …

Subcortical brain alterations in carriers of genomic copy number variants

K Kumar, C Modenato, C Moreau… - American Journal of …, 2023 - Am Psychiatric Assoc
Objective: Copy number variants (CNVs) are well-known genetic pleiotropic risk factors for
multiple neurodevelopmental and psychiatric disorders (NPDs), including autism (ASD) and …

Genetic heterogeneity shapes brain connectivity in psychiatry

CA Moreau, A Harvey, K Kumar, G Huguet… - Biological …, 2023 - Elsevier
Background Polygenicity and genetic heterogeneity pose great challenges for studying
psychiatric conditions. Genetically informed approaches have been implemented in …

Language profiles of school-aged children with 22q11. 2 copy number variants

J Verbesselt, CB Solot, E Van Den Heuvel, TB Crowley… - Genes, 2023 - mdpi.com
Although it is known that copy number variants (CNVs) on chromosome 22, such as 22q11.
2 deletion (22q11. 2DS) and 22q11. 2 duplication (22q11. 2Dup) syndromes, are associated …

Increased prevalence of rare copy number variants in treatment-resistant psychosis

M Farrell, TE Dietterich, MK Harner… - Schizophrenia …, 2023 - academic.oup.com
Background It remains unknown why~ 30% of patients with psychotic disorders fail to
respond to treatment. Previous genomic investigations of treatment-resistant psychosis have …

[HTML][HTML] Neuroimaging findings in neurodevelopmental copy number variants: identifying molecular pathways to convergent phenotypes

AI Silva, F Ehrhart, MO Ulfarsson, H Stefansson… - Biological …, 2022 - Elsevier
Genomic copy number variants (CNVs) are associated with a high risk of
neurodevelopmental disorders. A growing body of genetic studies suggests that these high …

Unraveling the link between CNVs, cognition and individual neuroimaging deviation scores from a population-based reference cohort

C Fraza, IE Sønderby, R Boen, Y Shi… - Nature Mental …, 2024 - nature.com
Copy number variations (CNVs) are genetic variants that can have a substantial influence
on neurodevelopment, neuropsychiatric traits and morphometric brain changes, yet their …