Osteogenesis imperfecta

A Forlino, JC Marini - The Lancet, 2016 - thelancet.com
Osteogenesis imperfecta is a phenotypically and molecularly heterogeneous group of
inherited connective tissue disorders that share similar skeletal abnormalities causing bone …

Osteogenesis imperfecta: clinical diagnosis, nomenclature and severity assessment

FS Van Dijk, DO Sillence - … journal of medical genetics Part A, 2014 - Wiley Online Library
Recently, the genetic heterogeneity in osteogenesis imperfecta (OI), proposed in 1979 by
Sillence et al., has been confirmed with molecular genetic studies. At present, 17 genetic …

Engineering a precise adenine base editor with minimal bystander editing

L Chen, S Zhang, N Xue, M Hong, X Zhang… - Nature Chemical …, 2023 - nature.com
Adenine base editors (ABEs) catalyze A-to-G transitions showing broad applications, but
their bystander mutations and off-target editing effects raise safety concerns. Through …

[HTML][HTML] Bone microenvironment regulative hydrogels with ROS scavenging and prolonged oxygen-generating for enhancing bone repair

H Sun, J Xu, Y Wang, S Shen, X Xu, L Zhang, Q Jiang - Bioactive materials, 2023 - Elsevier
Large bone defects resulting from fractures and disease are a major clinical challenge,
being often unable to heal spontaneously by the body's repair mechanisms. Lines of …

Extracellular matrix networks in bone remodeling

AI Alford, KM Kozloff, KD Hankenson - … journal of biochemistry & cell biology, 2015 - Elsevier
Bones are constantly remodeled throughout life to maintain robust structure and function.
Dysfunctional remodeling can result in pathological conditions such as osteoporosis (bone …

Osteogenesis imperfecta

JC Marini, WA Cabral - Genetics of bone biology and skeletal disease, 2018 - Elsevier
Osteogenesis imperfecta is a genetic disorder characterized by low bone mass, decreased
bone strength, increased bone fragility, and shortened stature. Autosomal dominant …

Developmental defects of enamel and dentine: challenges for basic science research and clinical management

WK Seow - Australian dental journal, 2014 - Wiley Online Library
Abnormalities of enamel and dentine are caused by a variety of interacting factors ranging
from genetic defects to environmental insults. The genetic changes associated with some …

Cell–matrix signals specify bone endothelial cells during developmental osteogenesis

UH Langen, ME Pitulescu, JM Kim… - Nature cell …, 2017 - nature.com
Blood vessels in the mammalian skeletal system control bone formation and support
haematopoiesis by generating local niche environments. While a specialized capillary …

Mutations in WNT1 cause different forms of bone fragility

K Keupp, F Beleggia, H Kayserili, AM Barnes… - The American Journal of …, 2013 - cell.com
We report that hypofunctional alleles of WNT1 cause autosomal-recessive osteogenesis
imperfecta, a congenital disorder characterized by reduced bone mass and recurrent …

Osteoporosis in children and adolescents: when to suspect and how to diagnose it

S Ciancia, RR van Rijn, W Högler… - European journal of …, 2022 - Springer
Early recognition of osteoporosis in children and adolescents is important in order to
establish an appropriate diagnosis of the underlying condition and to initiate treatment if …