VEXAS syndrome

PC Grayson, BA Patel, NS Young - Blood, The Journal of the …, 2021 - ashpublications.org
VEXAS syndrome (vacuoles, E1 enzyme, X-linked, autoinflammatory, somatic) is a
monogenic disease of adulthood caused by somatic mutations in UBA1 in hematopoietic …

Clonal haematopoiesis and dysregulation of the immune system

R Belizaire, WJ Wong, ML Robinette… - Nature Reviews …, 2023 - nature.com
Age-related diseases are frequently linked to pathological immune dysfunction, including
excessive inflammation, autoreactivity and immunodeficiency. Recent analyses of human …

[HTML][HTML] Somatic Mutations in UBA1 and Severe Adult-Onset Autoinflammatory Disease

DB Beck, MA Ferrada, KA Sikora… - … England Journal of …, 2020 - Mass Medical Soc
Background Adult-onset inflammatory syndromes often manifest with overlap** clinical
features. Variants in ubiquitin-related genes, previously implicated in autoinflammatory …

Benign and malignant hematologic manifestations in patients with VEXAS syndrome due to somatic mutations in UBA1

IE Obiorah, BA Patel, EM Groarke, W Wang… - Blood …, 2021 - ashpublications.org
Somatic mutations in UBA1 involving hematopoietic stem and myeloid cells have been
reported in patients with the newly defined VEXAS (vacuoles, E1 enzyme, X-linked …

Novel somatic mutations in UBA1 as a cause of VEXAS syndrome

JA Poulter, JC Collins, C Cargo… - Blood, The Journal …, 2021 - ashpublications.org
Novel somatic mutations in UBA1 as a cause of VEXAS syndrome | Blood | American Society of
Hematology Skip to Main Content Advertisement Umbrella Alt Text Umbrella Alt Text Close ASH …

An update on VEXAS syndrome

A Al-Hakim, S Savic - Expert Review of Clinical Immunology, 2023 - Taylor & Francis
Introduction VEXAS (vacuoles, E1 enzyme, X-linked, autoinflammatory, somatic) syndrome
is a recently described, late-onset, acquired autoinflammatory disorder caused by mutations …

A Phase II prospective trial of azacitidine in steroid-dependent or refractory systemic autoimmune/inflammatory disorders and VEXAS syndrome associated with MDS …

A Mekinian, LP Zhao, S Chevret, K Desseaux, L Pascal… - Leukemia, 2022 - nature.com
Systemic autoimmune and inflammatory disorders (SAID) are underestimated, and
potentially life-threatening complications observed in 15-25% of myelodysplastic neoplasms …

Novel causative variants of VEXAS in UBA1 detected through whole genome transcriptome sequencing in a large cohort of hematological malignancies

M Sakuma, P Blombery, M Meggendorfer, C Haferlach… - Leukemia, 2023 - nature.com
UBA1 is an X-linked gene and encodes an ubiquitin-activating enzyme. Three somatic
mutations altering the alternative start codon (M41) in UBA1 in hematopoietic precursor cells …

Early activation of inflammatory pathways in UBA1-mutated hematopoietic stem and progenitor cells in VEXAS

Z Wu, S Gao, Q Gao, BA Patel, EM Groarke, X Feng… - Cell Reports …, 2023 - cell.com
Summary VEXAS (vacuoles, E1 enzyme, X-linked, autoinflammatory, somatic) syndrome is a
pleiotropic, severe autoinflammatory disease caused by somatic mutations in the ubiquitin …

Relapsing polychondritis can be characterized by three different clinical phenotypes: analysis of a recent series of 142 patients

J Dion, N Costedoat‐Chalumeau, D Sène… - Arthritis & …, 2016 - Wiley Online Library
Objective Relapsing polychondritis (RP) is a rare condition characterized by recurrent
inflammation of cartilaginous tissue and systemic manifestations. Data on this disease …