Impaired p53-mediated DNA damage response contributes to microcephaly in Nijmegen Breakage Syndrome patient-derived cerebral organoids

S Martins, L Erichsen, A Datsi, W Wruck, W Goering… - Cells, 2022 - mdpi.com
Nijmegen Breakage Syndrome (NBS) is a rare autosomal recessive genetic disorder caused
by mutations within nibrin (NBN), a DNA damage repair protein. Hallmarks of NBS include …

Nijmegen breakage syndrome fibroblasts and iPSCs: cellular models for uncovering disease-associated signaling pathways and establishing a screening platform for …

B Mlody, W Wruck, S Martins, K Sperling, J Adjaye - Scientific Reports, 2017 - nature.com
Abstract Nijmegen Breakage Syndrome (NBS) is associated with cancer predisposition,
premature aging, immune deficiency, microcephaly and is caused by mutations in the gene …

Chromosomal instability and molecular defects in induced pluripotent stem cells from Nijmegen breakage syndrome patients

T Halevy, S Akov, M Bohndorf, B Mlody, J Adjaye… - Cell reports, 2016 - cell.com
Nijmegen breakage syndrome (NBS) results from the absence of the NBS1 protein,
responsible for detection of DNA double-strand breaks (DSBs). NBS is characterized by …

Investigating BPDE-induced embryonic toxicity employing hiPSC-based models

VC Meira de Amorim, A Lofrano, LP Szepanowski… - bioRxiv, 2024 - biorxiv.org
Benzo [a] pyrene diol epoxide (BPDE) is a metabolite of the environmental contaminant
Benzo [a] pyrene-a byproduct of incomplete combustion of organic matter. BPDE reacts with …

[HTML][HTML] Generation of an iPSC line (UMGWi001-B) from a patient with Floating-Harbor Syndrome (FLHS) carrying a heterozygous SRCAP mutation (p. Arg2444)

M Franz, L Hagenau, R Koch, S Neubauer, B Nowack… - Stem Cell Research, 2020 - Elsevier
Floating-Harbor syndrome (FLHS) is a rare genetic disease caused by mutations in the
SRCAP gene. Here, we generated an induced pluripotent stem cell line from gingival …

DNA damage signaling, cell reprogramming, and differentiation

M Shimada, T Miyake - Epigenetics and DNA Damage, 2022 - Elsevier
Genome stability is maintained by several molecular systems, eg, DNA repair, DNA
replication, DNA recombination, cell cycle checkpoint, and apoptosis. Recent evidence …