A genetic-pathophysiological framework for craniosynostosis

SRF Twigg, AOM Wilkie - The American Journal of Human Genetics, 2015 - cell.com
Craniosynostosis, the premature fusion of one or more cranial sutures of the skull, provides
a paradigm for investigating the interplay of genetic and environmental factors leading to …

Biology of bone formation, fracture healing, and distraction osteogenesis

CM Runyan, KS Gabrick - Journal of Craniofacial Surgery, 2017 - journals.lww.com
Distraction osteogenesis is a bone-regenerative process in which an osteotomy is followed
by distraction of the surrounding vascularized bone segments, with formation of new bone …

Two locus inheritance of non-syndromic midline craniosynostosis via rare SMAD6 and common BMP2 alleles

AT Timberlake, J Choi, S Zaidi, Q Lu… - elife, 2016 - elifesciences.org
Premature fusion of the cranial sutures (craniosynostosis), affecting 1 in 2000 newborns, is
treated surgically in infancy to prevent adverse neurologic outcomes. To identify mutations …

Understanding craniosynostosis as a growth disorder

K Flaherty, N Singh… - Wiley Interdisciplinary …, 2016 - Wiley Online Library
Craniosynostosis is a condition of complex etiology that always involves the premature
fusion of one or multiple cranial sutures and includes various anomalies of the soft and hard …

Tooth formation and eruption–lessons learnt from cleidocranial dysplasia

S Kreiborg, BL Jensen - European journal of oral sciences, 2018 - Wiley Online Library
The principles of formation, renewal, and eruption of teeth are discussed. Numerous genetic
aberrations may affect the formation and eruption of teeth. Cleidocranial dysplasia (CCD) …

Reduced dosage of ERF causes complex craniosynostosis in humans and mice and links ERK1/2 signaling to regulation of osteogenesis

SRF Twigg, E Vorgia, SJ McGowan, I Peraki… - Nature …, 2013 - nature.com
The extracellular signal–related kinases 1 and 2 (ERK1/2) are key proteins mediating
mitogen-activated protein kinase signaling downstream of RAS: phosphorylation of ERK1/2 …

Genetic advances in craniosynostosis

W Lattanzi, M Barba, L Di Pietro… - American journal of …, 2017 - Wiley Online Library
Craniosynostosis, the premature ossification of one or more skull sutures, is a clinically and
genetically heterogeneous congenital anomaly affecting approximately one in 2,500 live …

Genetics of nonsyndromic craniosynostosis

AT Timberlake, JA Persing - Plastic and reconstructive surgery, 2018 - journals.lww.com
Occurring once in every 2000 live births, craniosynostosis is one of the most frequent
congenital anomalies encountered by the craniofacial surgeon. Syndromic …

A genome-wide association study identifies susceptibility loci for nonsyndromic sagittal craniosynostosis near BMP2 and within BBS9

CM Justice, G Yagnik, Y Kim, I Peter, EW Jabs… - Nature …, 2012 - nature.com
Sagittal craniosynostosis is the most common form of craniosynostosis, affecting
approximately one in 5,000 newborns. We conducted, to our knowledge, the first genome …

Recent advances in craniosynostosis

E Yilmaz, E Mihci, B Nur, ÖM Alper, Ş Taçoy - Pediatric Neurology, 2019 - Elsevier
Craniosynostosis is a pathologic craniofacial disorder and is defined as the premature
fusion of one or more cranial (calvarial) sutures. Cranial sutures are fibrous joints consisting …