The importance of ongoing international surveillance for Creutzfeldt–Jakob disease

N Watson, JP Brandel, A Green, P Hermann… - Nature Reviews …, 2021‏ - nature.com
Creutzfeldt–Jakob disease (CJD) is a rapidly progressive, fatal and transmissible
neurodegenerative disease associated with the accumulation of misfolded prion protein in …

Towards a treatment for genetic prion disease: trials and biomarkers

SM Vallabh, EV Minikel, SL Schreiber… - The Lancet …, 2020‏ - thelancet.com
Prion disease is a rare, fatal, and exceptionally rapid neurodegenerative disease. Although
incurable, prion disease follows a clear pathogenic mechanism, in which a single gene …

Brainwide silencing of prion protein by AAV-mediated delivery of an engineered compact epigenetic editor

EN Neumann, TM Bertozzi, E Wu, F Serack, JW Harvey… - Science, 2024‏ - science.org
Prion disease is caused by misfolding of the prion protein (PrP) into pathogenic self-
propagating conformations, leading to rapid-onset dementia and death. However …

Evaluating drug targets through human loss-of-function genetic variation

EV Minikel, KJ Karczewski, HC Martin, BB Cummings… - Nature, 2020‏ - nature.com
Naturally occurring human genetic variants that are predicted to inactivate protein-coding
genes provide an in vivo model of human gene inactivation that complements knockout …

Effect of neprilysin inhibition on Alzheimer disease plasma biomarkers: a secondary analysis of a randomized clinical trial

WS Brum, KF Docherty, NJ Ashton, H Zetterberg… - JAMA …, 2024‏ - jamanetwork.com
Methods| In a post hoc exploratory analysis of a 52-week randomized clinical trial
(NCT03552575), we examined the effect of sacubitril/valsartan vs valsartan (ie, neprilysin …

Identification of novel risk loci and causal insights for sporadic Creutzfeldt-Jakob disease: a genome-wide association study

E Jones, H Hummerich, E Viré, J Uphill… - The Lancet …, 2020‏ - thelancet.com
Background Human prion diseases are rare and usually rapidly fatal neurodegenerative
disorders, the most common being sporadic Creutzfeldt-Jakob disease (sCJD). Variants in …

[HTML][HTML] Genetic counseling for prion disease: updates and best practices

JS Goldman, SM Vallabh - Genetics in Medicine, 2022‏ - Elsevier
Prion disease is a rare, fatal, and often rapidly progressive neurodegenerative disease. Ten
to fifteen percent of cases are caused by autosomal dominant gain-of-function variants in the …

Smart Nanoscale Extracellular Vesicles in the Brain: Unveiling their Biology, Diagnostic Potential, and Therapeutic Applications

A Onkar, F Khan, A Goenka… - … Applied Materials & …, 2024‏ - ACS Publications
Information exchange is essential for the brain, where it communicates the physiological and
pathological signals to the periphery and vice versa. Extracellular vesicles (EVs) are a …

Genetic aspects of human prion diseases

BS Appleby, S Shetty, M Elkasaby - Frontiers in Neurology, 2022‏ - frontiersin.org
Human prion diseases are rapidly progressive and fatal neurodegenerative conditions
caused by a disease-causing isoform of the native prion protein. The prion protein gene …

[HTML][HTML] Regional variability and genotypic and pharmacodynamic effects on PrP concentration in the CNS

MA Mortberg, HT Zhao, AG Reidenbach, JE Gentile… - JCI insight, 2022‏ - ncbi.nlm.nih.gov
Prion protein (PrP) concentration controls the kinetics of prion replication and is a genetically
and pharmacologically validated therapeutic target for prion disease. In order to evaluate …