Mutational signature analyses in multi-child families reveal sources of age-related increases in human germline mutations

H Shojaeisaadi, A Schoenrock, MJ Meier… - Communications …, 2024 - nature.com
Whole-genome sequencing studies of parent–offspring trios have provided valuable insights
into the potential impact of de novo mutations (DNMs) on human health and disease …

A maternal germline mutator phenotype in a family affected by heritable colorectal cancer

CL Young, AC Beichman, D Mas Ponte, SL Hemker… - Genetics, 2024 - academic.oup.com
Variation in DNA repair genes can increase cancer risk by elevating the rate of oncogenic
mutation. Defects in one such gene, MUTYH, are known to elevate the incidence of …

de novo variant calling identifies cancer mutation signatures in the 1000 Genomes Project

JK Ng, P Vats, E Fritz‐Waters, S Sarkar… - Human …, 2022 - Wiley Online Library
Detection of de novo variants (DNVs) is critical for studies of disease‐related variation and
mutation rates. To accelerate DNV calling, we developed a graphics processing units‐based …

Unprecedented female mutation bias in the aye-aye, a highly unusual lemur from Madagascar

RJ Wang, Y Peña-García, M Raveendran… - PLoS …, 2025 - journals.plos.org
Every mammal studied to date has been found to have a male mutation bias: male parents
transmit more de novo mutations to offspring than female parents, contributing increasingly …

Patterns and distribution of de novo mutations in multiplex Middle Eastern families

M Kohailan, W Aamer, N Syed, S Padmajeya… - Journal of Human …, 2022 - nature.com
While de novo mutations (DNMs) are key to genetic diversity, they are also responsible for a
high number of rare disorders. To date, no study has systematically examined the rate and …

Deciphering the role of germline complex de novo structural variations in rare disorders

H Jung, TP Yang, S Walker, P Danecek, IG Salinas… - bioRxiv, 2024 - biorxiv.org
De novo structural variants (dnSVs) have emerged as crucial genetic factors in the context of
rare disorders. However, these variations often go undiagnosed in routine genetic screening …

Low mutation rate but high male-bias in the germline of a short-lived opossum

Y Pena-Garcia, R Wang, M Raveendran, RA Harris… - bioRxiv, 2024 - biorxiv.org
Age and sex have been found to be important determinants of the mutation rate per
generation in mammals, but the mechanisms underlying these factors are still unclear. One …

de novo variant calling identifies cancer mutation profiles in the 1000 Genomes Project

JK Ng, P Vats, E Fritz-Waters, S Sarkar, EI Sams… - bioRxiv, 2021 - biorxiv.org
Detection of de novo variants (DNVs) is critical for studies of disease-related variation and
mutation rates. We developed a GPU-based workflow to rapidly call DNVs (HAT) and …

Complex de novo structural variants are an underestimated cause of rare disorders

R Rahbari, H Jung, TP Yang, S Walker, P Danecek… - 2024 - researchsquare.com
Complex de novo structural variants (dnSVs) are crucial genetic factors in rare disorders, yet
their prevalence and characteristics in rare disorders remain poorly understood. Here, we …

Parental germline mosaicism in genome-wide phased de novo variants: recurrence risk assessment and implications for precision genetic counselling

F Lecoquierre, N Drouot, S Coutant, O Quenez… - 2024 - researchsquare.com
Background: De novo mutations (DNMs) significantly impact health, particularly through
developmental disorders. DNMs occur in both paternal and maternal germlines via diverse …