[HTML][HTML] A 25-year odyssey of genomic technology advances and structural variant discovery

D Porubsky, EE Eichler - Cell, 2024 - cell.com
This perspective focuses on advances in genome technology over the last 25 years and
their impact on germline variant discovery within the field of human genetics. The field has …

Precision medicine in rare diseases: What is next?

B Tesi, C Boileau, KM Boycott… - Journal of internal …, 2023 - Wiley Online Library
Molecular diagnostics is a cornerstone of modern precision medicine, broadly understood
as tailoring an individual's treatment, follow‐up, and care based on molecular data. In rare …

[HTML][HTML] Inverted triplications formed by iterative template switches generate structural variant diversity at genomic disorder loci

CM Grochowski, JD Bengtsson, H Du, M Gandhi… - Cell Genomics, 2024 - cell.com
The duplication-triplication/inverted-duplication (DUP-TRP/INV-DUP) structure is a complex
genomic rearrangement (CGR). Although it has been identified as an important pathogenic …

Long-read genome sequencing and variant reanalysis increase diagnostic yield in neurodevelopmental disorders

SM Hiatt, JMJ Lawlor, LH Handley, DR Latner… - Genome …, 2024 - genome.cshlp.org
Variant detection from long-read genome sequencing (lrGS) has proven to be more accurate
and comprehensive than variant detection from short-read genome sequencing (srGS) …

Cost-effectiveness of whole-genome vs whole-exome sequencing among children with suspected genetic disorders

MC Nurchis, FC Radio, L Salmasi… - JAMA network …, 2024 - jamanetwork.com
Importance The diagnosis of rare diseases and other genetic conditions can be daunting
due to vague or poorly defined clinical features that are not recognized even by experienced …

Chromosomal instability in genome evolution: From cancer to macroevolution

V Comaills, M Castellano-Pozo - Biology, 2023 - mdpi.com
Simple Summary The experimental/pathological observation of genome chaos (including
massive and large-scale translocations, chromothripsis, and polyploidy cancer cells) …

Truvari: refined structural variant comparison preserves allelic diversity

AC English, VK Menon, RA Gibbs, GA Metcalf… - Genome Biology, 2022 - Springer
The fundamental challenge of multi-sample structural variant (SV) analysis such as merging
and benchmarking is identifying when two SVs are the same. Common approaches for …

Resolving complex duplication variants in autism spectrum disorder using long-read genome sequencing

J Eisfeldt, EJ Higginbotham, F Lenner, J Howe… - Genome …, 2024 - genome.cshlp.org
Rare or de novo structural variation, primarily in the form of copy number variants, is
detected in 5%–10% of autism spectrum disorder (ASD) families. While complex structural …

[HTML][HTML] Real-world diagnostic outcomes and cost-effectiveness of genome-wide sequencing for developmental and seizure disorders: evidence from Canada

DA Regier, R Loewen, B Chan, M Ehman, S Pollard… - Genetics in …, 2024 - Elsevier
Purpose To determine real-world diagnostic rates, cost trajectories, and cost-effectiveness of
exome sequencing (ES) and genome sequencing (GS) for children with developmental …