Update on clinical gene therapy for hemophilia

GQ Perrin, RW Herzog… - Blood, The Journal of the …, 2019 - ashpublications.org
In contrast to other diverse therapies for the X-linked bleeding disorder hemophilia that are
currently in clinical development, gene therapy holds the promise of a lasting cure with a …

Gene therapy for hemophilia: what does the future hold?

BS Doshi, VR Arruda - Therapeutic advances in hematology, 2018 - journals.sagepub.com
Recent phase I/II adeno-associated viral vector-mediated gene therapy clinical trials have
reported remarkable success in ameliorating disease phenotype in hemophilia A and B …

A molecular revolution in the treatment of hemophilia

JSS Butterfield, KM Hege, RW Herzog, R Kaczmarek - Molecular Therapy, 2020 - cell.com
For decades, the monogenetic bleeding disorders hemophilia A and B (coagulation factor
VIII and IX deficiency) have been treated with systemic protein replacement therapy. Now …

Clinical advances in gene therapy updates on clinical trials of gene therapy in haemophilia

F Peyvandi, I Garagiola - Haemophilia, 2019 - Wiley Online Library
Gene therapy is rapidly becoming a new therapeutic strategy for haemophilia A and B
treatment. In the 1990s, studies in animal models showed that adeno‐associated vectors …

[HTML][HTML] Deciphering conundrums of adeno-associated virus liver-directed gene therapy: focus on hemophilia

GF Pierce, S Fong, BR Long, R Kaczmarek - Journal of Thrombosis and …, 2024 - Elsevier
Adeno-associated virus gene therapy has been the subject of intensive investigation for
monogenic disease gene addition therapy for more than 25 years, yet few therapies have …

Protein-engineered coagulation factors for hemophilia gene therapy

BJ Samelson-Jones, VR Arruda - Molecular Therapy-Methods & Clinical …, 2019 - cell.com
Hemophilia A (HA) and hemophilia B (HB) are X-linked bleeding disorders due to
inheritable deficiencies in either coagulation factor VIII (FVIII) or factor IX (FIX), respectively …

AAV gene therapy in companion dogs with severe hemophilia: Real-world long-term data on immunogenicity, efficacy, and quality of life

BS Doshi, BJ Samelson-Jones, TC Nichols… - … Therapy Methods & …, 2024 - cell.com
The hemophilias are the most common severe inherited bleeding disorders and are caused
by deficiency of clotting factor (F) VIII (hemophilia A) or FIX (hemophilia B). The resultant …

Cellular stress and coagulation factor production: when more isn't necessarily better

Z Chen, RW Herzog, RJ Kaufman - Journal of Thrombosis and …, 2023 - Elsevier
Remarkably, it has been 40 years since the isolation of the two genes involved in
hemophilia A (HA) and hemophilia B (HB), encoding clotting factors VIII (FVIII) and IX (FIX) …

Activated protein C has a regulatory role in factor VIII function

AR Wilhelm, NA Parsons… - Blood, The Journal …, 2021 - ashpublications.org
Mechanisms thought to regulate activated factor VIII (FVIIIa) cofactor function include A2-
domain dissociation and activated protein C (APC) cleavage. Unlike A2-domain …

Analysis of vector genome integrations in multicentric lymphoma after AAV gene therapy in a severe hemophilia A dog

L Van Gorder, BS Doshi, E Willis, TC Nichols… - … Therapy Methods & …, 2023 - cell.com
Adeno-associated viral (AAV) vectors have traditionally been viewed as predominantly
nonintegrating, with limited concerns for oncogenesis. However, accumulating preclinical …