Spinocerebellar ataxia

T Klockgether, C Mariotti, HL Paulson - Nature reviews Disease primers, 2019 - nature.com
The spinocerebellar ataxias (SCAs) are a genetically heterogeneous group of autosomal
dominantly inherited progressive disorders, the clinical hallmark of which is loss of balance …

Polyglutamine diseases

EL Bunting, J Hamilton, SJ Tabrizi - Current Opinion in Neurobiology, 2022 - Elsevier
Polyglutamine diseases are a collection of nine CAG trinucleotide expansion disorders,
presenting with a spectrum of neurological and clinical phenotypes. Recent human, mouse …

Cell-type-specific CAG repeat expansions and toxicity of mutant Huntingtin in human striatum and cerebellum

K Mätlik, M Baffuto, L Kus, AL Deshmukh, DA Davis… - Nature …, 2024 - nature.com
Brain region-specific degeneration and somatic expansions of the mutant Huntingtin (mHTT)
CAG tract are key features of Huntington's disease (HD). However, the relationships among …

Patterns of CAG repeat instability in the central nervous system and periphery in Huntington's disease and in spinocerebellar ataxia type 1

R Mouro Pinto, L Arning, JV Giordano… - Human molecular …, 2020 - academic.oup.com
The expanded HTT CAG repeat causing Huntington's disease (HD) exhibits somatic
expansion proposed to drive the rate of disease onset by eliciting a pathological process …

Whole-genome landscape of adult T-cell leukemia/lymphoma

Y Kogure, T Kameda, J Koya… - Blood, The Journal …, 2022 - ashpublications.org
Adult T-cell leukemia/lymphoma (ATL) is an aggressive neoplasm immunophenotypically
resembling regulatory T cells, associated with human T-cell leukemia virus type-1. Here, we …

[HTML][HTML] Antisense oligonucleotide–mediated ataxin-1 reduction prolongs survival in SCA1 mice and reveals disease-associated transcriptome profiles

J Friedrich, HB Kordasiewicz, B O'Callaghan… - JCI insight, 2018 - ncbi.nlm.nih.gov
Abstract Spinocerebellar ataxia type 1 (SCA1) is a dominantly inherited ataxia caused by
expansion of a translated CAG repeat encoding a glutamine tract in the ataxin-1 (ATXN1) …

Disruption of the ATXN1-CIC complex reveals the role of additional nuclear ATXN1 interactors in spinocerebellar ataxia type 1

SL Coffin, MA Durham, L Nitschke, E Xhako, AM Brown… - Neuron, 2023 - cell.com
Summary Spinocerebellar ataxia type 1 (SCA1) is a paradigmatic neurodegenerative
disease in that it is caused by a mutation in a broadly expressed protein, ATXN1; however …

Uninterrupted CAG repeat drives striatum-selective transcriptionopathy and nuclear pathogenesis in human Huntingtin BAC mice

X Gu, J Richman, P Langfelder, N Wang, S Zhang… - Neuron, 2022 - cell.com
In Huntington's disease (HD), the uninterrupted CAG repeat length, but not the
polyglutamine length, predicts disease onset. However, the underlying pathobiology …

Sequence composition changes in short tandem repeats: heterogeneity, detection, mechanisms and clinical implications

IS Rajan-Babu, E Dolzhenko, MA Eberle… - Nature Reviews …, 2024 - nature.com
Short tandem repeats (STRs) are a class of repetitive elements, composed of tandem arrays
of 1–6 base pair sequence motifs, that comprise a substantial fraction of the human genome …

Aberrant cerebellar circuitry in the spinocerebellar ataxias

KJ Robinson, M Watchon, AS Laird - Frontiers in neuroscience, 2020 - frontiersin.org
The spinocerebellar ataxias (SCAs) are a heterogeneous group of neurodegenerative
diseases that share convergent disease features. A common symptom of these diseases is …