Update of variants identified in the pancreatic β‐cell KATP channel genes KCNJ11 and ABCC8 in individuals with congenital hyperinsulinism and diabetes

E De Franco, C Saint‐Martin, K Brusgaard… - Human …, 2020‏ - Wiley Online Library
The most common genetic cause of neonatal diabetes and hyperinsulinism is pathogenic
variants in ABCC8 and KCNJ11. These genes encode the subunits of the β‐cell ATP …

[HTML][HTML] Potassium channels in behavioral brain disorders. Molecular mechanisms and therapeutic potential: a narrative review.

KA Alam, P Svalastoga, A Martinez, JC Glennon… - Neuroscience & …, 2023‏ - Elsevier
Abstract Potassium channels (K+-channels) selectively control the passive flow of potassium
ions across biological membranes and thereby also regulate membrane excitability. Genetic …

[PDF][PDF] ISPAD Clinical Practice Consensus Guidelines 2018: The diagnosis and management of monogenic diabetes in children and adolescents

AT Hattersley, SAW Greeley, M Polak… - 2018‏ - ore.exeter.ac.uk
Monogenic diabetes results from one or more defects in a single gene. The disease may be
inherited within families as a dominant, recessive or non-Mendelian trait or may present as a …

[HTML][HTML] ISPAD Clinical Practice Consensus Guidelines 2022: The diagnosis and management of monogenic diabetes in children and adolescents

SAW Greeley, M Polak, PR Njølstad, F Barbetti… - Pediatric …, 2022‏ - ncbi.nlm.nih.gov
ISPAD Clinical Practice Consensus Guidelines 2022: The diagnosis and management of
monogenic diabetes in children and adolescents - PMC Back to Top Skip to main content NIH …

[HTML][HTML] The effect of early, comprehensive genomic testing on clinical care in neonatal diabetes: an international cohort study

E De Franco, SE Flanagan, JAL Houghton, HL Allen… - The Lancet, 2015‏ - thelancet.com
Background Traditional genetic testing focusses on analysis of one or a few genes
according to clinical features; this approach is changing as improved sequencing methods …

Switching from insulin to oral sulfonylureas in patients with diabetes due to Kir6. 2 mutations

ER Pearson, I Flechtner, PR Njølstad… - … England Journal of …, 2006‏ - Mass Medical Soc
Background Heterozygous activating mutations in KCNJ11, encoding the Kir6. 2 subunit of
the ATP-sensitive potassium (KATP) channel, cause 30 to 58 percent of cases of diabetes …

Using SIFT and PolyPhen to predict loss-of-function and gain-of-function mutations

SE Flanagan, AM Patch, S Ellard - Genetic testing and molecular …, 2010‏ - liebertpub.com
Context: The interpretation of novel missense variants is a challenge with increasing
numbers of such variants being identified and a responsibility to report the findings in the …

Activating Mutations in the ABCC8 Gene in Neonatal Diabetes Mellitus

AP Babenko, M Polak, H Cavé, K Busiah… - … England Journal of …, 2006‏ - Mass Medical Soc
Background The ATP-sensitive potassium (KATP) channel, composed of the beta-cell
proteins sulfonylurea receptor (SUR1) and inward-rectifying potassium channel subunit Kir6 …

Macrosomia and Hyperinsulinaemic Hypoglycaemia in Patients with Heterozygous Mutations in the HNF4A Gene

ER Pearson, SF Boj, AM Steele, T Barrett, K Stals… - PLoS …, 2007‏ - journals.plos.org
Background Macrosomia is associated with considerable neonatal and maternal morbidity.
Factors that predict macrosomia are poorly understood. The increased rate of macrosomia in …

[PDF][PDF] The diagnosis and management of monogenic diabetes in children and adolescents.

O Rubio‐Cabezas, AT Hattersley, PR Njølstad… - Pediatric diabetes, 2014‏ - bnsde.org
Monogenic diabetes results from one or more defects in a single gene. The disease may be
inherited within families as a dominant, recessive, or non-Mendelian trait or may present as …