ALS genetics, mechanisms, and therapeutics: where are we now?

R Mejzini, LL Flynn, IL Pitout, S Fletcher… - Frontiers in …, 2019 - frontiersin.org
The scientific landscape surrounding amyotrophic lateral sclerosis (ALS) continues to shift
as the number of genes associated with the disease risk and pathogenesis, and the cellular …

An update on the neurological short tandem repeat expansion disorders and the emergence of long-read sequencing diagnostics

SR Chintalaphani, SS Pineda, IW Deveson… - Acta Neuropathologica …, 2021 - Springer
Background Short tandem repeat (STR) expansion disorders are an important cause of
human neurological disease. They have an established role in more than 40 different …

Therapeutic reduction of ataxin-2 extends lifespan and reduces pathology in TDP-43 mice

LA Becker, B Huang, G Bieri, R Ma, DA Knowles… - Nature, 2017 - nature.com
Amyotrophic lateral sclerosis (ALS) is a rapidly progressing neurodegenerative disease that
is characterized by motor neuron loss and that leads to paralysis and death 2–5 years after …

[HTML][HTML] Antisense Oligonucleotides for the Study and Treatment of ALS

BD Boros, KM Schoch, CJ Kreple, TM Miller - Neurotherapeutics, 2022 - Elsevier
Amyotrophic lateral sclerosis (ALS) is a fatal neurodegenerative disease characterized by
motor neuron loss. ALS is now associated with mutations in numerous genes, many of which …

Update on recent advances in amyotrophic lateral sclerosis

N Riva, T Domi, L Pozzi, C Lunetta, P Schito… - Journal of …, 2024 - Springer
In the last few years, our understanding of disease molecular mechanisms underpinning
ALS has advanced greatly, allowing the first steps in translating into clinical practice novel …

Value of systematic genetic screening of patients with amyotrophic lateral sclerosis

SR Shepheard, MD Parker, J Cooper-Knock… - Journal of Neurology …, 2021 - jnnp.bmj.com
Objective The clinical utility of routine genetic sequencing in amyotrophic lateral sclerosis
(ALS) is uncertain. Our aim was to determine whether routine targeted sequencing of 44 …

Short tandem repeat expansions in sporadic amyotrophic lateral sclerosis and frontotemporal dementia

L Henden, LG Fearnley, N Grima, EP McCann… - Science …, 2023 - science.org
Pathogenic short tandem repeat (STR) expansions cause over 20 neurodegenerative
diseases. To determine the contribution of STRs in sporadic amyotrophic lateral sclerosis …

[HTML][HTML] Emerging therapies and novel targets for TDP-43 proteinopathy in ALS/FTD

LR Hayes, P Kalab - Neurotherapeutics, 2022 - Elsevier
Nuclear clearance and cytoplasmic mislocalization of the essential RNA binding protein,
TDP-43, is a pathologic hallmark of amyotrophic lateral sclerosis, frontotemporal dementia …

ATAXIN-2 intermediate-length polyglutamine expansions elicit ALS-associated metabolic and immune phenotypes

R Vieira de Sá, E Sudria-Lopez… - Nature …, 2024 - nature.com
Intermediate-length repeat expansions in ATAXIN-2 (ATXN2) are the strongest genetic risk
factor for amyotrophic lateral sclerosis (ALS). At the molecular level, ATXN2 intermediate …

[HTML][HTML] The genetic architecture of ALS

A Shatunov, A Al-Chalabi - Neurobiology of disease, 2021 - Elsevier
Amyotrophic lateral sclerosis (ALS) is a heterogeneous group of neurological conditions
which have in common the progressive degeneration of upper and lower motor neurons …